Congenital midline cervical cleft (literature survey and description of own clinical observations)
DOI:
https://doi.org/10.15574/PS.2023.79.85Keywords:
cervical cleft, congenital defect, childrenAbstract
Midline cervical cleft - (synonym: webbed neck, pterygium colli medianum, neck ugliness), belongs to rare congenital defects which, unfortunately, have not been widely covered in the specialized medical literature at the modern stage of the development of medicine. It is confirmed by the fact that until 2014 according to the literature search there were a little over 100 detailed descriptions of the respective pathology.
Purpose - to summarize the experience accumulated by experts in order to understand deeper all the aspects of Congenital midline cervical cleft, to introduce the present position of this rare congenital malformation to colleagues, to learn the structural parts of this pathology and the tactic for its treatment.
The article represents the last data from scientific literature about Congenital midline cervical cleft and the analytic results of the two medical cases with this congenital malformation in children. Studying these cases, we used general clinical tests and histological research for the removal tissues.
Conclusions. The current lack of information on the midline cervical cleft as well as the results of histological examinations in different clinical cases confirm the necessity of further study of this rare congenital defect. In this case, a deeper analysis of embryological, genetic and environmental factors influencing the process of formation of this pathology can be of help. In our opinion, performing the surgery becomes appropriate before two-year age in order to prevent the relapse of this pathology and severe neck contractures in the future.
The study was carried out in accordance with the principles of the Helsinki declaration. The informed consent of the patient was obtained for conducting the studies.
No conflict of interests was declared by the authors.
References
Aboaziza A, Akpan U. (2018). Newborn with Neck Lesion. NeoReviews. 19 (10): e633-e635. https://doi.org/10.1542/neo.19-10-e633
Agrawal V, Sanghvi BV, Borwankar SS. (2009). Congenital Midline Cervical Cleft: A Case Report. The Internet Journal of Surgery. 22 (1): 1-3. https://doi.org/10.5580/956
Celikoyar M, Aktan E, Dogusoy G. (2019). Congenital midline cervical cleft: a case report. Journal of Medical Case Reports. 13 (1): 1-4. https://doi.org/10.1186/s13256-019-2116-6; PMid:31176376 PMCid:PMC6556223
Eom TK, Sun H, Yoon HK. (2014). Congenital midline cervical cleft. Archives of plastic surgery. 41 (4): 429-431. https://doi.org/10.5999/aps.2014.41.4.429; PMid:25075373 PMCid:PMC4113710
Fan Y, Matthews H, Kilpatrick N, Claes P, Clement J, Penington A. (2018). 4 Facial morphology and growth following surgery for congenital midline cervical cleft patients. International Journal of Oral and Maxillofacial Surgery. 47 (4): 437-441. https://doi.org/10.1016/j.ijom.2017.12.006; PMid:29373199
Farhadi R, Alam SA, Ghasemi M. (2012). Case report: congenital midline cervical cleft: can it be treated in newborn? Iranian Journal of Pediatrics. 4 (22): 547-550.
Helal AA, Mahmoud BA. (2018). Congenital midline cervical cleft. Journal of pediatric surgery case reports. 36: 3-6. https://doi.org/10.1016/j.epsc.2018.06.007
King J, Patel RV, Huddart SN. (2013). Congenital midline cervical cleft. Journal of Pediatric Surgery Case Reports. 1 (5): 99-101. https://doi.org/10.1016/j.epsc.2013.04.002
Macaj M, Jovankovicova A, Jakubikova J, Koller J. (2016). A case of untreated midline cervical cleft associated with congenital heart defect. Case Studies in Surgery. 1 (2): 60-63. https://doi.org/10.5430/css.v2n1p60
Mirza B. (2013). Congenital midline cervical cleft. APSP Journal of Case Reports. 4 (1): 9.
Oshi AME, Al-Sofiani MM, Abdulbasit OB, Al Bhlal LA, Seidahmed MZ. (2015). Congenital midline cervical cleft: case report and literature review. Journal of Clinical Neonatology. 4(4): 278-280. https://doi.org/10.4103/2249-4847.161720
Rodriguez ÁHR, Guimarães ASC, de Abreu e Souza RR, Padrão TM, de Souza ANF. (2012). Congenital midline cervical cleft. Revista Brasileira de Cirurgia Plástica. 27: 644-647. https://doi.org/10.1590/S1983-51752012000400031
Sinopidis X, Kourea HP, Panagidis A, Alexopoulos V, Tzifas S, Dimitriou G, Georgiou G. (2012). Congenital midline cervical cleft: diagnosis, pathologic findings, and early stage treatment. Case Reports in Pediatrics: 951040. https://doi.org/10.1155/2012/951040; PMid:23094176 PMCid:PMC3474213
Downloads
Published
Issue
Section
License
Copyright (c) 2023 Paediatric Surgery (Ukraine)
This work is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License.
The policy of the Journal “PAEDIATRIC SURGERY. UKRAINE” is compatible with the vast majority of funders' of open access and self-archiving policies. The journal provides immediate open access route being convinced that everyone – not only scientists - can benefit from research results, and publishes articles exclusively under open access distribution, with a Creative Commons Attribution-Noncommercial 4.0 international license(СС BY-NC).
Authors transfer the copyright to the Journal “PAEDIATRIC SURGERY.UKRAINE” when the manuscript is accepted for publication. Authors declare that this manuscript has not been published nor is under simultaneous consideration for publication elsewhere. After publication, the articles become freely available on-line to the public.
Readers have the right to use, distribute, and reproduce articles in any medium, provided the articles and the journal are properly cited.
The use of published materials for commercial purposes is strongly prohibited.